TY - JOUR
T1 - Hyperactive and impulsive behaviors of LMTK1 knockout mice
AU - Takahashi, Miyuki
AU - Sugiyama, Arika
AU - Wei, Ran
AU - Kobayashi, Shizuka
AU - Fukuda, Kimiko
AU - Nishino, Hironori
AU - Takahashi, Roka
AU - Tsutsumi, Koji
AU - Kita, Ichiro
AU - Ando, Kanae
AU - Manabe, Toshiya
AU - Kamiguchi, Hiroyuki
AU - Tomomura, Mineko
AU - Hisanaga, Shin ichi
N1 - Funding Information:
We thank Dr. K. Yamada at Riken for Morris water maze and fear condition tests, Dr. I. Uemura at Tokyo Metropolitan University for electron microscopic technique, Dr. M. Itakura at Kitasato University for providing anti-VAMP-2 antibody, Dr. M. Taniguchi at Medical University of South Carolina for discussion on behavior experiments. This work was supported in part by MEXT Grant-in-aid project, Scientific Research on Innovation Area (Brain Protein Aging and Dementia Control) of Japan (26117004 to S. H.), by a grant-in-aid MEXT (16K07060 to S.H.), by a grant from JSPS to MT (16J05051), and by The Uehara Memorial Foundation.
Publisher Copyright:
© 2020, The Author(s).
PY - 2020/12/1
Y1 - 2020/12/1
N2 - Lemur tail kinase 1 (LMTK1), previously called Apoptosis-Associated Tyrosine Kinase (AATYK), remains an uncharacterized Ser/Thr protein kinase that is predominantly expressed in the brain. It is recently reported that LMTK1A, an isoform of LMTK1, binds to recycling endosomes through its palmitoylation and regulates endosomal trafficking by suppressing the activity of Rab11 small GTPase. In neurons, knockdown or knockout of LMTK1 results in longer axons, greater branching of dendrites and increased number of spines, suggesting that LMTK1 plays a role in neuronal circuit formation. However, its in vivo function remained to be investigated. Here, we examined the brain structures and behaviors of LMTK1 knockout (KO) mice. LMTK1 was expressed in most neurons throughout the brain. The overall brain structure appeared to be normal in LMTK1 KO mice, but the numbers of synapses were increased. LMTK1 KO mice had a slight impairment in memory formation and exhibited distinct psychiatric behaviors such as hyperactivity, impulsiveness and high motor coordination without social interaction deficits. Some of these abnormal behaviors represent core features of attention deficit hyperactive disorder (ADHD), suggesting the possible involvement of LMTK1 in the pathogenesis of ADHD.
AB - Lemur tail kinase 1 (LMTK1), previously called Apoptosis-Associated Tyrosine Kinase (AATYK), remains an uncharacterized Ser/Thr protein kinase that is predominantly expressed in the brain. It is recently reported that LMTK1A, an isoform of LMTK1, binds to recycling endosomes through its palmitoylation and regulates endosomal trafficking by suppressing the activity of Rab11 small GTPase. In neurons, knockdown or knockout of LMTK1 results in longer axons, greater branching of dendrites and increased number of spines, suggesting that LMTK1 plays a role in neuronal circuit formation. However, its in vivo function remained to be investigated. Here, we examined the brain structures and behaviors of LMTK1 knockout (KO) mice. LMTK1 was expressed in most neurons throughout the brain. The overall brain structure appeared to be normal in LMTK1 KO mice, but the numbers of synapses were increased. LMTK1 KO mice had a slight impairment in memory formation and exhibited distinct psychiatric behaviors such as hyperactivity, impulsiveness and high motor coordination without social interaction deficits. Some of these abnormal behaviors represent core features of attention deficit hyperactive disorder (ADHD), suggesting the possible involvement of LMTK1 in the pathogenesis of ADHD.
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U2 - 10.1038/s41598-020-72304-z
DO - 10.1038/s41598-020-72304-z
M3 - Article
C2 - 32963255
AN - SCOPUS:85091313885
SN - 2045-2322
VL - 10
JO - Scientific reports
JF - Scientific reports
IS - 1
M1 - 15461
ER -